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“Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter Hagoort Dieke Lagers-vanHaselen & colleagues from Rotterdam Erasmus Universiteit Rotterdam, Dept. of Neuroscience, July 14, 2005
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“Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

Mar 31, 2015

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Page 1: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

“Kikker, waar ben je?” Narratives in Dutch speakers with

Williams syndrome

Barbara SchmiedtováPeter Indefrey

Monique Flecken, Neeltje VerstegenPeter Hagoort

Dieke Lagers-vanHaselen & colleagues from Rotterdam

Erasmus Universiteit Rotterdam, Dept. of Neuroscience, July 14, 2005

Page 2: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

2

Outline

I. Recapitulation of project’s goalsII. Populations

- examples: chat format

III. Coding procedures- examples of coding categories

IV. Results- comparison to English results

V. Discussion

Page 3: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

3

General research question

How general intellectual impairment with a specific genetic basis may affect the process oflanguage acquisitionandnarrative development?

Page 4: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

4

Focus on Narratives

• typical development– morphosyntactic structures acquired by age 5

(e.g. Gretsch 2001, Bowerman 1992, Slobin 1985)

BUT– application of morphosyntactic forms in

discourse, that is considering information & temporal structure, much later (Halm 2005, age 14)

Page 5: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

5

Dissociation between language and cognition

• Williams syndrome– distinct behavioral phenotype (Bellugi et at. 2000,

1999)

– mild to moderate retardation: IQ 55 (rarely reaching above 80)

– productive language skills preserved (in contrast to other genetic syndromes with mental retardation, e.g. Down Syndrome)

– extremely social and outgoing personality

Page 6: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

6

Populations

• PatientsWilliams syndrome (N= 51)

Pseudo-Williams (N=8)

• Control groupsTypically developing children (N=49)

- IQ matched sample: 5-6 year olds

Adults (N=72)- Age matched sample: 15-18 year olds

Page 7: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Transcription & Coding

Patients: 2460 propositions

Adults: 4032 propositions

Children: 2254 propositions

Total: 8746 propositions

Page 8: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

8

Coding procedures

• coding scheme (Reilly et al. 2004, 1998)

– 4 domains:

1. the overall story length

2. grammatical competence

3. narrative skills (episodic & thematic)

4. evaluation devices

Page 9: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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1. Story Length

• In general, narratives vary in length => number of propositionsa proposition = predicate and its arguments

Coding criteria:1. Same subject?2. Two separate sentences?3. Do two clauses realize one/two events?

Page 10: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Number of propositions - examples

• One proposition“De jongen kruipt in de boom om te zien …..” (prop1)

• Two propositions “De volgende ochtend zien ze dus (prop1)

dat de kikker weg is.” (prop 2)

Page 11: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

11

2. Grammatical Competence

A) Morphological Errors, e.g. (27 categories in total)

• Errors in pronouns (*hem heeft de kikker gevonden)• Omissions of auxiliaries and/or verbs (*kikker

weggelopen)• Verb tense (*toen loopt…)• Omission of determiners and gender errors (*het

jongetje, die…)• Noun plurals (*de bijs)• Number marking (*de jongen en de hond loopt)• Prepositional errors (*roepen achter)• Omission of ‘er’ / ‘te’• Word order errors• Omission of verbs/ non-existing words / too many words

Page 12: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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2. Gram. Competence - cont’

B) Occurrences of complex syntax

• Coordinate sentences (maar, en, of)• Adverbial sentences (toen, want)• Verb complements (zien dat + X, proberen te +

V, beginnen te + V)• Relative clauses• Passives

Page 13: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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3. Narrative skills

• Thematic (0-4)– Maintenance of story theme

• Frog missing & boy looking for him (0-2)

• Theme reiterated throughout the story0 - no additional mentions;2 - multiple additional mentions

Page 14: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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3. Narrative skills – cont’

• Episodic (0-8)– Basic components of the story

1. Settings

2. Instantiation

3. – 7. The five main search episodes

8. The story’s resolution

Page 15: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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4. Evaluation devices

1. Cognitive inferences (“De jongen denkt …”)

2. Social engagement(“Oooh, wat gebeurt er nou weer?”)

3. Affective states and/or behaviors(“De jongen mist zijn kikker, wat zielig!”)

4. Intensifiers + repetitions(“De jongen roept heel erg hard”)

5. Indication of certainty/uncertainty (“Misschien zit de kikker wel in die boom”)

Page 16: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Analyses

• Comparisons– Williams syndrome (WMS) vs. typically developing

children (TD) vs. adults (AD)– In some cases Pseudo-WMS subjects included– Dutch (WMS vs. TD) & English (WMS vs. TD)

• Compensation for the length of the story– Number of countable categories divided by

number of propositions

Page 17: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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English Data Set

• Reilly et al., Brain and Language (88),2004, 229 - 247– Main focus on development in children– 3 different age groups – Comparisons

• SLI vs. TD• WMS vs. TD• SLI vs. TD• FL (unilateral focal brain lesions) vs. TD• SLI vs. FL

Page 18: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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1. Length of Story:number of propositions

0

10

20

30

40

50

60

Nr. of Propositions

Me

an

Nr.

of

oc

cu

rre

nc

es

AdultsChildrenWMSPseudo

*

p < .05

English Data Set: no difference between TD vs. WMS

ENG NL

Page 19: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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2. Grammatical skills: morphological errors

0

10

20

30

40

50

60

70

Morphological ErrorsMe

an

Nr.

of

Mo

rph

olo

gic

al E

rro

rs

AdultsChildrenWMSPseudo

p < .05

*

English Data Set: strong difference between TD vs. WMS

ENG NL

Page 20: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

20

2. Grammatical skills:complex syntax

0

10

20

30

40

50

60

70

80

Complex Syntax

Me

an

of

Nr.

of

oc

cu

rre

nc

es

AdultChildrenWMSPseudo

p < .05

*

ENG NL

English Data Set: strong difference between TD vs. WMS

Page 21: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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3. Narrative structure:Theme Maintenance

0

1

2

3

4

Theme Maintenance (0-4)

Me

an

Sc

ore Adults

ChildrenWMSPseudo

p < .05

*

English Data Set: strong difference between TD vs. WMS

ENG NL

Page 22: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

22

3. Narrative structure:Story components

0

1

2

3

4

5

6

7

8

Story components (0-8)

Me

an

Sc

ore Adults

ChildrenWMSPseudo

p < .05

*

*

English Data Set: strong difference between TD vs. WMS

ENG NL

Page 23: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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4. Evaluation devices

05

101520253035404550

Evaluation Devices

Me

an

of

Nr.

of

oc

cu

rre

nc

es

AdultsChildrenWMSPseudo

p < .05

*

*

English Data Set: strong difference between TD vs. WMS

ENG NL

Page 24: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Summary:Dutch vs. English WMS

No differences– Nr. of propositions– Grammatical

competence• Morphological errors• Complex syntax

– Narrative skills• Story components

Differences– Narrative skills

• Story maintenance

WMS groups together with TD children

Age related?

Page 25: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Dutch WMS: age groups

32%

32%

36%

young:< 12middle: 12 - 19 older: ≥ 20

Page 26: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Dutch WMS: Age & Theme maintenance

0

1

2

3

4

Theme maintenance

Me

an

Sc

ore

YoungMiddleOlder

p < .05

* young vs. middle, young vs. older; n.s. middle vs. older

*

Page 27: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Dutch WMS: Age & Story components

0

1

2

3

4

5

6

7

8

Theme maintenance

Me

an

Sc

ore

YoungMiddleOlder

* young vs. middle, young vs. older; n.s. middle vs. older

*

p < .05

Page 28: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Dutch WMS:Age & Number of propositions

0

10

20

30

40

50

60

Number of Propositions

Me

an

Nr.

of

oc

cu

rre

nc

es

YoungMiddleOlder

* young vs. middle, young vs. older; n.s. middle vs. older

*

p < .05

Page 29: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

29

Dutch WMS:Age & Evaluation Devices

0

10

20

30

40

50

60

70

Evaluation Devices

Me

an

Nr.

of

oc

cu

rre

nc

es

YoungMiddleOlder

* young vs. middle, young vs. older; n.s. middle vs. older

*

p < .05

Page 30: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

30

Dutch WMS:No changes with Age

• WMS ”weak“ points– Grammatical competence

• In all age groups, a very high number of morphological errors

• Complex syntax: stable number of syntactic structures (=> no increase in complexity when the story length goes up with age!)

Page 31: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Summary: age in WMS

Developmental changes in WMS: Critical period between the age of 12 and 19

• Changes inMaintenance of Theme - better

Story length – stories longer (BUT not more complex)

Evaluation Devices – fewer

Page 32: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

32

Dutch WMS:Age & Blokpatronen (BP)

0

5

10

15

20

25

BP Score

Mea

n S

core

YoungMiddleOlder

* young vs. older; n.s. young vs. middle & middle vs. older

*

p < .05

Page 33: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

33

Dutch WMS:Age & Boston Naming Test (BNT)

0

10

20

30

40

BNT Score

Mea

n S

core

YoungMiddleOlder

*

p < .05

* young vs. middle, young vs. older; n.s. middle vs. older

Page 34: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

34

Dutch WMS:Age & Peabody Picture Vocabulary Test (PPVT)

0

20

40

60

80

100

120

140

PPVT

Mea

n S

core

YoungMiddleOlder

*

p < .05

* young vs. middle, young vs. older; n.s. middle vs. older

Page 35: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Summary: development in Dutch WMS & other tests

Development in all three investigated tests• Blokpatronen• Boston Naming Test• Peabody Picture Vocabulary Test

Page 36: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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Future plans

• More correlations between the Frog- story-measurements & other tests

• Investigation diversity in each category (token/type ratio)

Page 37: “Kikker, waar ben je?” Narratives in Dutch speakers with Williams syndrome Barbara Schmiedtová Peter Indefrey Monique Flecken, Neeltje Verstegen Peter.

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THANK YOU!